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Isolated congenital inter-costal pulmonary hernia: a case report.

ABSTRACT:

Background

Intercostal lung herniation is a rare condition that may be congenital (20%) or acquired (80%). The isolated congenital form is exceptional, with one case reported in the literature.

Case presentation

We report a case of a 10-year-old French boy of Algeria origin, born with intermittent swelling of his right hemithorax. The swelling and pain gradually increased with age. A clinical examination revealed a localized swelling of his right hemithorax at the level of the midclavicular line and the fifth intercostal space. The swelling increased in size during respiratory movements and enlarged with Valsalva maneuvers. The intercostal lung hernia was treated by thoracoscopy.

Conclusions

This is the second case of isolated congenital intercostal pulmonary hernia reported in the French and English literature. It is the first to be treated by thoracoscopy. Based on this case we performed a review of the diagnosis and therapeutic aspect of pulmonary hernias.

SUBMITTER: Tapsoba TW

PROVIDER: S-EPMC6637642 | biostudies-literature | 2019 Jul

REPOSITORIES: biostudies-literature

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Isolated congenital inter-costal pulmonary hernia: a case report.

Tapsoba Toussain Wendlamita TW Grapin-Dagorno Christine C Bonnard Arnaud A El-Ghoneimi Alaa A

Journal of medical case reports 20190718 1

<h4>Background</h4>Intercostal lung herniation is a rare condition that may be congenital (20%) or acquired (80%). The isolated congenital form is exceptional, with one case reported in the literature.<h4>Case presentation</h4>We report a case of a 10-year-old French boy of Algeria origin, born with intermittent swelling of his right hemithorax. The swelling and pain gradually increased with age. A clinical examination revealed a localized swelling of his right hemithorax at the level of the mid ...[more]

PMID: 31315682

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